Idiopathic Hypereosinophilic Syndrome Presenting with Recalcitrant Oral and Genital Ulcers Responding Well to Thalidomide

被引：0

作者：

Srinivas, Sahana M. ^{[1
,3
]}

Chebbi, Pooja G. ^{[2
]}

Shivappa, Sanjay K. ^{[1
]}

机构：

[1] Indira Gandhi Inst Child Hlth, Dept Pediat Dermatol, Bengaluru, Karnataka, India

[2] Indira Gandhi Inst Child Hlth, Dept Pediat Med, Bengaluru, Karnataka, India

[3] Indira Gandhi Inst Child Hlth, Dept Pediat Dermatol, Bengaluru 560001, Karnataka, India

来源：

INDIAN DERMATOLOGY ONLINE JOURNAL | 2023年 / 14卷 / 05期

关键词：

Hypereosinophilic syndrome; idiopathic; mucosal ulcers; recurrent;

D O I：

10.4103/idoj.idoj_632_22

中图分类号：

R75 [皮肤病学与性病学];

学科分类号：

100206 ;

摘要：

Hypereosinophilic syndrome is a myeloproliferative disorder characterized by abnormal accumulation of eosinophils in the blood or peripheral tissues. It is uncommonly seen in children. We describe a 14-year-old girl diagnosed with idiopathic hypereosinophilic syndrome presenting with recurrent, painful oral and genital ulcers, hepatosplenomegaly along with consistently high eosinophil count and leucocytosis. Genetic studies showed negative for FIPIL-PDGFRA fusion gene. Mucosal ulcers were recalcitrant to conventional therapy and responded well to thalidomide.

引用

页码：676 / 678

页数：3

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