Ochronotic arthropathy in the context of spondyloarthritis differential diagnosis: a case-based review

被引:3
|
作者
Kostova, Tsvetelina [1 ]
Batalov, Zguro [1 ]
Karalilova, Rositsa [1 ]
Batalov, Anastas [1 ]
机构
[1] Med Univ Plovdiv, Dept Propaedeut Internal Med, Plovdiv, Bulgaria
关键词
Alkaptonuria; Ochronosis; Ochronotic arthropathy; Spondyloarthritis; ALKAPTONURIA; INVOLVEMENT; JOINT;
D O I
10.1007/s00296-022-05191-4
中图分类号
R5 [内科学];
学科分类号
1002 ; 100201 ;
摘要
Alkaptonuria is a disease often forgotten because of its rarity. Its pathogenic mechanism is the deficiency of one of the enzymes of the tyrosine degradation pathway-homogentisate-1, 2-dioxygenase, which sequelae is accumulation and deposition of its metabolite homogentisic acid in connective tissues and urine. Alkaptonuria presents as a clinical triad-darkening urine upon prolonged exposure to air, pigmentation of connective tissues and debilitating arthropathy. We present a case report of a 67-year old patient with alkaptonuria who presented with the clinical triad, but was mistakenly diagnosed as having ankylosing spondylitis in the past. Currently there is no treatment for the disease hence the management strategy was focused on symptoms control with analgesics, physical therapy, dietary modification, vitamin C supplementation, and joint arthroplasty. Alkaptonuria's clinical features are extensively described in the literature and despite the fact that it is a rare disease, due to the similar radiographic changes with spondyloarthropathies, it should be included in the differential diagnosis in young patients presenting with severe joint involvement. Early recognition of the disease is necessary since its natural evolution is joint destruction leading to significant reduction in the quality of life. Alkaptonuria's articular features in the spine and peripheral tissues are well described using the classical imaging techniques. Musculoskeletal ultrasonography shows a characteristic set of findings in the soft tissues, including synovium, cartilage, tendons and entheses.
引用
收藏
页码:2277 / 2282
页数:6
相关论文
共 50 条
  • [31] Pediatrics - A Case-Based Review
    Jain, Agam
    Lodha, Rakesh
    INDIAN JOURNAL OF PEDIATRICS, 2020, 87 (07): : 574 - 574
  • [32] Case-Based Review: meningioma
    Fogh, Shannon E.
    Johnson, Derek R.
    Barker, Fred G., II
    Brastianos, Priscilla K.
    Clarke, Jennifer L.
    Kaufmann, Timothy J.
    Oberndorfer, Stephan
    Preusser, Matthias
    Raghunathan, Aditya
    Santagata, Sandro
    Theodosopoulos, Philip V.
    NEURO-ONCOLOGY PRACTICE, 2016, 3 (02) : 120 - 134
  • [33] Mastoiditis: A case-based review
    Wang, NE
    Burg, JM
    PEDIATRIC EMERGENCY CARE, 1998, 14 (04) : 290 - 292
  • [34] Pediatrics: A Case-Based Review
    Dietrick, Barbara A.
    Stafstrom, Carl E.
    JOURNAL OF PEDIATRIC EPILEPSY, 2020, 09 (02) : 55 - 56
  • [35] CASE-BASED REASONING - A REVIEW
    WATSON, I
    MARIR, F
    KNOWLEDGE ENGINEERING REVIEW, 1994, 9 (04): : 327 - 354
  • [36] THE DIAGNOSIS OF HERPESENCEPHALITIS - A CASE-BASED UPDATE
    Csonka Tamas
    Szepesi Rita
    Bidiga Laszlo
    Peter Mozes
    Klekner Almos
    Hutoczky Gabor
    Csiba Laszlo
    Mehes Gabor
    Hortobagyi Tibor
    IDEGGYOGYASZATI SZEMLE-CLINICAL NEUROSCIENCE, 2013, 66 (9-10): : 337 - 342
  • [37] Fault diagnosis based on case-based reasoning
    Li Jimin
    Meng Xianguo
    PROCEEDINGS OF THE FIRST INTERNATIONAL SYMPOSIUM ON TEST AUTOMATION & INSTRUMENTATION, VOLS 1 - 3, 2006, : 954 - 957
  • [38] Case-based reasoning for diagnosis applications
    Goeker, Mehmet H.
    Howlett, Robert J.
    Price, Joseph E.
    KNOWLEDGE ENGINEERING REVIEW, 2005, 20 (03): : 277 - 281
  • [39] Case-based diagnosis of dysmorphic syndromes
    Waligora, T
    Schmidt, R
    BIOLOGICAL AND MEDICAL DATA ANALYSIS, PROCEEDINGS, 2004, 3337 : 79 - 84
  • [40] Non-steroidal hip arthropathy: case histories and differential diagnosis
    Kakar, S
    Jeffery, JA
    Bentley, G
    HOSPITAL MEDICINE, 2001, 62 (05): : 308 - 309