Pseudotumoral sublingual leishmaniasis caused by Leishmania infantum

Introduction. - Mucosat leishmaniasis is endemic in certain parts of Latin America and are usually absent in Morocco. Herein we report a case of Leishmania infantum in a Moroccan patient. Patients and methods. - A 61-year-old male patient working as a tourist bus driver presented with a sublingual endobuccat tumor. He reported a history of treated cutaneous leishmaniasis of the tower lip in 2009 and had presented the sublingual oral tumor since December 2011. The histopathological findings as welt as the species-specific PCR analysis confirmed the diagnosis of sublingual mucosal leishmaniasis due to L. infantum. HIV serology was negative. Our patient was then treated with intra-muscular meglumine antimoniate for 25 days, resulting in complete disappearance of the oral lesion. Conclusion. - Our case thus has several peculiarities: the strictly mucosal character of the lesion, occurring in an immunocompetent subject, the unusual pseudotumoral form, and the causative agent, L. infantum, not known for its mucosal tropism in our country. (C) 2020 Elsevier Masson SAS. All rights reserved.