Immunoglobulin G4 related disease isolated to the nasal cavity: a rare cause of nasal obstruction

被引：8
|
作者：
Morris, C. [1 ]
Ng, T. [2 ]
Kevin, P. [1 ]
Singh, N. [1 ]
机构：
[1] Univ Sydney, Westmead Hospital, Dept Otolaryngol Head & Neck Surg, Sydney, NSW 2145, Australia
[2] Westmead Hosp, ICPMR, Dept Tissue Pathol, Westmead, NSW 2145, Australia
来源：
JOURNAL OF LARYNGOLOGY AND OTOLOGY | 2015年 / 129卷
关键词：
IgG4; IgG4-Related Sclerosing Disease; IgG4-Related Disease; Nasal Cavity; Nasal Obstruction; Immunoglobulin G; Methotrexate; Autoimmune Disease; Eosinophils;
D O I：
10.1017/S0022215114001911
中图分类号：
R76 [耳鼻咽喉科学];
学科分类号：
100213 ;
摘要：
Background: Immunoglobulin G4 related disease is a rare condition. Cases involving the sinonasal region are exceptionally uncommon. This paper describes a case of immunoglobulin G4 related disease isolated solely to the nasal cavity. Methods: Case report and literature review. Results: A 34-year-old man presented with painless, progressive bilateral nasal obstruction. Clinical examination and imaging findings demonstrated bilateral submucosal swelling of the anterior septum and right external nasal wall. Biopsy revealed immunoglobulin G4 related disease. The patient responded to oral corticosteroids initially, followed by long-term methotrexate. Conclusion: To the best of our knowledge, this case represents the first report in the literature of immunoglobulin G4 related disease isolated solely to the nasal cavity.
引用
收藏
页码：S57 / S59
页数：3
相关论文
共 50 条
  • [21] The inverted Papilloma - a rare cause of Nasal Obstruction.
    Breining, T.
    Lindemann, J.
    Pauls, S.
    ROFO-FORTSCHRITTE AUF DEM GEBIET DER RONTGENSTRAHLEN UND DER BILDGEBENDEN VERFAHREN, 2009, 181 (06): : 599 - 600
  • [22] BILATERAL NASOLABIAL CYST: A RARE CAUSE OF NASAL OBSTRUCTION
    Choudhary, Samir
    JOURNAL OF EVOLUTION OF MEDICAL AND DENTAL SCIENCES-JEMDS, 2015, 4 (86): : 15105 - 15109
  • [23] Inferior Turbinate osteoma - rare cause of nasal obstruction
    Kumar, K. Krishna
    Sumathi, V.
    Sundhari, V.
    INDIAN JOURNAL OF OTOLARYNGOLOGY AND HEAD & NECK SURGERY, 2010, 62 (03) : 332 - 334
  • [24] Local Nasal 'Protective' Immunoglobulin G4 (IgG4) Responses in Nasal Fluid Following Grass Pollen Sublingual Immunotherapy
    Saleem, Nausheen
    Chaker, Adam
    Zissler, Ulrich
    Schmidt-Weber, Carsten B.
    Durham, Stephen R.
    Shamji, Mohamed H.
    JOURNAL OF ALLERGY AND CLINICAL IMMUNOLOGY, 2013, 131 (02) : AB202 - AB202
  • [25] Immunoglobulin G4 and Related Diseases
    Sthoeger, Zev
    Asher, Ilan
    Rosenberg-Bezalel, Shira
    Mahlab-Guri, Keren
    ISRAEL MEDICAL ASSOCIATION JOURNAL, 2012, 14 (10): : 642 - 645
  • [26] Congenital nasal pyriform aperture stenosis: a rare cause of neonatal nasal airway obstruction
    Rao, A.
    Godehal, S. M.
    Patil, A. R.
    Mallarajapatna, G.
    Nandikoor, S.
    Hariharan, M.
    BJR CASE REPORTS, 2015, 1 (01):
  • [27] RITUXIMAB TREATMENT FOR REFRACTORY IMMUNOGLOBULIN G4 RELATED DISEASE
    Casian, Alina
    Sanglel, Shirish
    O'Brien, Tim
    Fernando, Archie
    Stanford, Miles
    D'Cruz, David
    RHEUMATOLOGY, 2018, 57
  • [28] Dual Manifestations of Immunoglobulin G4 Related Disease in Thorax
    Subramaniam, S.
    Mahender, H.
    Mariappan, S.
    AMERICAN JOURNAL OF RESPIRATORY AND CRITICAL CARE MEDICINE, 2018, 197
  • [29] Serum Immunoglobulin G4 Level Is a Poor Predictor of Immunoglobulin G4-Related Disease
    Ngwa, Taiwo N.
    Law, Ryan
    Murray, David
    Chari, Suresh T.
    PANCREAS, 2014, 43 (05) : 704 - 707
  • [30] Monotypic angiomyolipoma of the nasal cavity: An extremely rare cause of nasal mass with recurrent epistaxis
    Pandey, Vinita
    Khatib, Yasmeen
    Gupte, Prajakta
    Pandey, Rahul
    Khare, Manisha S.
    INDIAN JOURNAL OF PATHOLOGY AND MICROBIOLOGY, 2020, 63 (01) : 106 - 108
12345