Loss-of-function variant in DNASE1L3 causes a familial form of systemic lupus erythematosus

被引:347
|
作者
Al-Mayouf, Sulaiman M. [2 ]
Sunker, Asma [1 ]
Abdwani, Reem [3 ]
Al Abrawi, Safiya [4 ]
Almurshedi, Fathiya [5 ]
Alhashmi, Nadia [4 ]
Al Sonbul, Abdullah [2 ]
Sewairi, Wafaa [6 ,7 ]
Qari, Aliya [8 ]
Abdallah, Eiman [3 ]
Al-Owain, Mohammed [8 ,9 ]
Al Motywee, Saleh [6 ,7 ]
Al-Rayes, Hanan [10 ]
Hashem, Mais [1 ]
Khalak, Hanif [1 ]
Al-Jebali, Latifa [1 ]
Alkuraya, Fowzan S. [1 ,9 ,11 ,12 ]
机构
[1] King Faisal Specialist Hosp & Res Ctr, Dept Genet, Riyadh 11211, Saudi Arabia
[2] King Faisal Specialist Hosp & Res Ctr, Dept Pediat, Rheumatol Sect, Riyadh 11211, Saudi Arabia
[3] Sultan Qaboos Univ Hosp, Dept Child Hlth, Muscat, Oman
[4] Royal Hosp, Dept Child Hlth, Muscat, Oman
[5] Sultan Qaboos Univ Hosp, Dept Genet, Muscat, Oman
[6] King Fahad Natl Guard Hosp, Div Rheumatol, Dept Med, Riyadh, Saudi Arabia
[7] King Abdullah Int Med Res Ctr, Riyadh, Saudi Arabia
[8] King Faisal Specialist Hosp & Res Ctr, Dept Med Genet, Riyadh, Saudi Arabia
[9] Alfaisal Univ, Coll Med, Dept Anat & Cell Biol, Riyadh, Saudi Arabia
[10] Riyadh Mil Hosp, Dept Med, Riyadh, Saudi Arabia
[11] King Saud Univ, Coll Med, Riyadh 11461, Saudi Arabia
[12] King Khalid Univ Hosp, Dept Pediat, Riyadh 11472, Saudi Arabia
关键词
SUSCEPTIBILITY VARIANTS; DEOXYRIBONUCLEASE I; PXK;
D O I
10.1038/ng.975
中图分类号
Q3 [遗传学];
学科分类号
071007 ; 090102 ;
摘要
Systemic lupus erythematosus (SLE) is a complex autoimmune disease that causes substantial morbidity. As is typical for many other multifactorial disorders, much of the heritability of SLE remains unknown. We identified a rare autosomal recessive form of SLE, in which autozygome analysis revealed a null mutation in the DNASE1L3 gene. The DNASE1L3-related SLE we describe was always pediatric in onset and correlated with a high frequency of lupus nephritis. Our findings confirm the critical role of impaired clearance of degraded DNA in SLE pathogenesis.
引用
收藏
页码:1186 / 1188
页数:3
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