Laryngeal stenosis in a patient with severe congenital neutropenia

被引：0
|
作者：
Bando, Hideki [1 ]
Nagao, Hikaru [1 ]
Nishio, Takeshi [1 ]
Hirota, Ryuichi [1 ]
Sakaguchi, Hirofumi [1 ]
Imamura, Toshihiko [2 ]
Hisa, Yasuo [1 ]
机构：
[1] Kyoto Prefectural Univ Med, Dept Otolaryngol Head & Neck Surg, Kyoto 6028566, Japan
[2] Kyoto Prefectural Univ Med, Dept Pediat, Kyoto 6028566, Japan
来源：
LARYNGOSCOPE | 2013年 / 123卷 / 02期
关键词：
Larynx; stenosis; Kostmann; severe congenital neutropenia;
D O I：
10.1002/lary.23375
中图分类号：
R-3 [医学研究方法]; R3 [基础医学];
学科分类号：
1001 ;
摘要：
Objectives/Hypothesis: We report the first case of laryngeal stenosis with granuloma in a patient with severe congenital neutropenia (SCN). Study Design: Case report and retrospective review. Methods: Review of medical records. Results: A 6-year-old female who was diagnosed with SCN presented with a cough and wheezing. An endoscopic study revealed laryngeal stenosis with granuloma. Tracheotomy and direct laryngoscopy were performed under general anesthesia, and administration of granulocyte colony-stimulating factor was started. The laryngeal granuloma disappeared 3 weeks later, and the tracheal stoma was closed. Conclusions: Presence of a laryngeal lesion should be considered in SCN patients with persistent airway symptoms.
引用
收藏
页码：455 / 457
页数：3
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