Unusual case of pulmonary renal syndrome with autopsy findings

被引:2
|
作者
Sonia, Badwal [1 ]
Jyoti, Kotwal [1 ]
Prakash, Varma Prem [2 ]
机构
[1] Armed Forces Med Coll, Dept Pathol, Pune 411040, Maharashtra, India
[2] Army Hosp Res & Referral, Dept Nephrol, Delhi, India
关键词
Diffuse alveolar hemorrhage; systemic sclerosis; thrombotic microangiopathy; SYSTEMIC-SCLEROSIS; SCLERODERMA; CRISIS; COMPLICATIONS;
D O I
10.4103/0377-4929.120403
中图分类号
R36 [病理学];
学科分类号
100104 ;
摘要
Scleroderma renal crises (SRC) is a serious complication of systemic sclerosis whose prognosis remains serious despite management with angiotensin-converting enzyme inhibitors, antihypertensives and dialysis. Pulmonary renal syndrome (PRS), characterised by diffuse alveolar hemorrhage (DAH) and SRC, is rare and carries a grave prognosis. This case report discusses the clinicopathological features of a 43-year-old male presenting with severe hypertension and rapidly progressive renal failure who subsequently developed DAH and died. The clinical course, exhaustive investigative work-up and autopsy findings led to a diagnosis of diffuse systemic sclerosis with PRS subcategorized into PRS with thrombotic microangiopathy. The index case came without a prior diagnosis of systemic sclerosis, thereby posing a serious diagnostic challenge and management issues.
引用
收藏
页码:294 / 296
页数:3
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