Case report of congenital neutropenia type 4 with glucose-6-phosphatase catalytic subunit 3 (G6PC3) deficiency

被引:0
|
作者
Dhayhi, Nabil S. [1 ]
Mahnashi, Mohammed A. [2 ]
Mokhasha, Alanoud I. [3 ]
Ahmed, Lana F. [3 ]
Shamakhi, Ahmed E. [4 ]
Ageel, Adeeb A. [5 ]
Tohary, Mohammed A. [5 ]
Alhazmi, Abdulaziz H. [6 ,7 ]
机构
[1] King Fahad Cent Hosp, Pediat Infect Dis Unit, Jazan, Saudi Arabia
[2] King Fahad Cent Hosp, Pediat Genet Dis Unit, Jazan, Saudi Arabia
[3] King Fahad Cent Hosp, Pediat Dept, Jazan, Saudi Arabia
[4] King Fahad Cent Hosp, Pediat Allergy Immunol Unit, Jazan, Saudi Arabia
[5] Kung Fahad Cent Hosp, Pediat Hematol Unit, Jazan, Saudi Arabia
[6] Jazan Univ, Fac Med, Jazan, Saudi Arabia
[7] Jazan Univ, Fac Med, Jazan 45142, Saudi Arabia
来源
CLINICAL CASE REPORTS | 2024年 / 12卷 / 02期
关键词
abscess; congenital neutropenia; Dursun syndrome; immune deficiency; Jazan; Saudi Arabia;
D O I
10.1002/ccr3.8540
中图分类号
R5 [内科学];
学科分类号
1002 ; 100201 ;
摘要
Congenital neutropenia syndromes encompass a group of genetic disorders characterized by persistent neutropenia and recurrent infections inherited in an autosomal recessive, dominant, or X-linked manner. These syndromes arise from mutations in various genes, and one of the significant genes involved is glucose-6-phosphatase catalytic subunit 3 (G6PC3), giving rise to a condition known as Dursun syndrome. As per existing knowledge, a total of 92 cases of Dursun syndrome have been reported globally, including eight cases from Saudi Arabia. Our study identified two additional cases exhibiting neutropenia since the early postnatal period and recurrent admissions due to infections. Additionally, these patients presented with oral ulcers, chronic diarrhea, and anomalies affecting the cardiac and genitourinary systems. The rising incidence of congenital neutropenia on a global scale necessitates heightened vigilance among clinicians to ensure thorough follow-up of patients with neutropenia. This proactive approach can lead to early detection and appropriate management of associated complications, ultimately improving patient outcomes.
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页数:4
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