A Pathogenic Variant of PBX1 Identified by Whole Exome Sequencing in a Chinese CAKUTHED Case

被引:3
|
作者
Nie, Ling [1 ]
Li, Yan [1 ]
Xiao, Tangli [1 ]
Zhang, Bo [1 ]
Zhao, Jinghong [1 ]
Hou, Weiping [1 ]
机构
[1] Army Med Univ, Mil Med Univ 3, Xinqiao Hosp, Dept Nephrol,Key Lab Prevent & Treatment Chron Kid, Chongqing, Peoples R China
关键词
CAKUTHED; PBX1; Pathogenic variant; Whole exome sequencing; Case report;
D O I
10.1159/000526847
中图分类号
R5 [内科学]; R69 [泌尿科学(泌尿生殖系疾病)];
学科分类号
1002 ; 100201 ;
摘要
Congenital anomalies of kidney and urinary tract syndrome with or without hearing loss, abnormal ears, or developmental delay (CAKUTHED) is a rare autosomal dominant disorder and variants in PBX1 are involved in the etiology of this syndrome. Precise diagnosis is difficult without genetic test. We described a Chinese CAKUTHED patient, whose characteristics were collected from medical records. The potential responsible variants were explored by whole exome sequencing. A heterozygous variant in the PBX1 gene (NM_002585 c.862C>T, p.R288*) was found in the proband, which was confirmed by Sanger sequencing. This heterozygous variant in the PBX1 gene was the molecular pathogenic basis of this disorder. It is necessary to perform a genetic test for diagnosing chronic nephritis with unknown reason.
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页码:311 / 315
页数:5
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