Acute acquired comitant esotropia associated with Lhermitte-Duclos disease: a case report
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作者:
Ota, Junya
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Hokkaido Univ, Fac Med, Dept Ophthalmol, Sapporo, Japan
Hokkaido Univ, Grad Sch Med, Sapporo, Japan
Sunagawa City Med Ctr, Dept Ophthalmol, Sunagawa, JapanHokkaido Univ, Fac Med, Dept Ophthalmol, Sapporo, Japan
Ota, Junya
[1
,2
,3
]
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Ando, Ryo
[1
,2
]
Motegi, Hiroaki
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Hokkaido Univ, Hokkaido Univ Sch Med, Dept Neurosurg, Sapporo, JapanHokkaido Univ, Fac Med, Dept Ophthalmol, Sapporo, Japan
Motegi, Hiroaki
[4
]
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Sugino, Hirokazu
[5
,6
]
Mitsuhashi, Tomoko
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Hokkaido Univ Hosp, Dept Surg Pathol, Sapporo, JapanHokkaido Univ, Fac Med, Dept Ophthalmol, Sapporo, Japan
Mitsuhashi, Tomoko
[5
]
Ishida, Susumu
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Hokkaido Univ, Fac Med, Dept Ophthalmol, Sapporo, Japan
Hokkaido Univ, Grad Sch Med, Sapporo, JapanHokkaido Univ, Fac Med, Dept Ophthalmol, Sapporo, Japan
Ishida, Susumu
[1
,2
]
机构:
[1] Hokkaido Univ, Fac Med, Dept Ophthalmol, Sapporo, Japan
[2] Hokkaido Univ, Grad Sch Med, Sapporo, Japan
[3] Sunagawa City Med Ctr, Dept Ophthalmol, Sunagawa, Japan
Acute acquired comitant esotropia;
Lhermitte-Duclos disease;
Papilledema;
Hydrocephalus;
A case report;
D O I:
10.1186/s13256-024-04683-0
中图分类号:
R5 [内科学];
学科分类号:
1002 ;
100201 ;
摘要:
BackgroundAcute acquired comitant esotropia caused by prolonged near work, such as the use of digital devices, has been frequently reported in recent years. However, intracranial examination is necessary even for patients with nonparalytic comitant esotropia. Lhermitte-Duclos disease is a rare tumor that grows in layers in the cerebellum. Among those with this disease, cases of esotropia have been reported due to abduction limitation of the eye, but there have been no reports of comitant esotropia. Here, we report the case of a young woman with acute acquired comitant esotropia who was found to have Lhermitte-Duclos disease.Case presentationA 16-year-old Japanese female patient, whose ethnicity was Asian, was referred to our hospital for acute acquired comitant esotropia. Fundus examination revealed papilledema in both eyes, and magnetic resonance imaging of the head revealed a cerebellar tumor in the right cerebellum with obstructive hydrocephalus. She underwent partial tumor resection, and a histopathological diagnosis of Lhermitte-Duclos disease was obtained. However, comitant esotropia status remained unchanged, and she underwent strabismus surgery. Finally, diplopia disappeared completely.ConclusionNeurological and intracranial imaging examinations are essential when acute acquired comitant esotropia is observed. Acute acquired comitant esotropia by Lhermitte-Duclos disease did not improve with partial tumor resection and required strabismus surgery, but good surgical results were obtained.
机构:
Hiroshima City Asa Hosp, Dept Neurosurg, Asakita Ku, Hiroshima 7310293, JapanHiroshima City Asa Hosp, Dept Neurosurg, Asakita Ku, Hiroshima 7310293, Japan
Isobe, N
Oki, S
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Hiroshima City Asa Hosp, Dept Neurosurg, Asakita Ku, Hiroshima 7310293, JapanHiroshima City Asa Hosp, Dept Neurosurg, Asakita Ku, Hiroshima 7310293, Japan
Oki, S
Murakami, T
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Hiroshima City Asa Hosp, Dept Neurosurg, Asakita Ku, Hiroshima 7310293, JapanHiroshima City Asa Hosp, Dept Neurosurg, Asakita Ku, Hiroshima 7310293, Japan
Murakami, T
Ooyama, S
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Hiroshima City Asa Hosp, Dept Neurosurg, Asakita Ku, Hiroshima 7310293, JapanHiroshima City Asa Hosp, Dept Neurosurg, Asakita Ku, Hiroshima 7310293, Japan
Ooyama, S
Kureshima, M
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Hiroshima City Asa Hosp, Dept Neurosurg, Asakita Ku, Hiroshima 7310293, JapanHiroshima City Asa Hosp, Dept Neurosurg, Asakita Ku, Hiroshima 7310293, Japan
Kureshima, M
Kurokawa, Y
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Hiroshima City Asa Hosp, Dept Neurosurg, Asakita Ku, Hiroshima 7310293, JapanHiroshima City Asa Hosp, Dept Neurosurg, Asakita Ku, Hiroshima 7310293, Japan