An unusual cause of gastric perforation in childhood: trichobezoar (Rapunzel syndrome). A case report

被引:15
|
作者
Koc, Orhan [2 ]
Yildiz, Fesih Dogan [3 ]
Narci, Adnan [1 ]
Sen, Tolga Altug [4 ]
机构
[1] Afyon Kocatepe Univ, Dept Pediat Surg, Fac Med, TR-03200 Afyon, Turkey
[2] Nazilli State Hosp, Pediat Surg Clin, Nazilli, Aydin, Turkey
[3] Nazilli State Hosp, Gen Surg Clin, Nazilli, Aydin, Turkey
[4] Afyon Kocatepe Univ, Dept Pediat, Fac Med, Afyon, Turkey
关键词
Child; Gastric perforation; Rapunzel syndrome; Trichobezoar; RAPUNZEL-SYNDROME; BEZOARS;
D O I
10.1007/s00431-008-0773-3
中图分类号
R72 [儿科学];
学科分类号
100202 ;
摘要
Trichobezoars are hair balls found in the stomach and formed following trichitillomania and trichopaghia. Rapunzel syndrome is a rare condition in which the presence of giant trichobezoars causes mechanical obstruction. To date, only two cases of stomach perforation caused by trichobezoars have been reported among pediatric patients. We report a 14-year-old female patient who experienced nausea, vomiting and severe abdominal pain for 1 month. Physical examination revealed diffuse abdominal distension. Palpation detected a mobile and sensitive mass, 15 x 15 cm , which filled the upper quadrant. Urgent surgery revealed that the stomach was perforated by the trichobezoar ball. This trichobezoar mass was totally excised by expanding the perforation area. Conclusion This is the reported third case of gastric perforation caused by trichobezoar in a pediatric patient. Among acute abdominal cases, gastric perforation should remain a possibility in differential diagnosis.
引用
收藏
页码:495 / 497
页数:3
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