Epibulbar osseous choristoma with dermolipoma: A case report and review of literature

被引:0
|
作者
Kim, Ju Mi [1 ]
Son, Woo Young [1 ]
Sul, Hae Joung [2 ]
Shin, Jeongah [1 ]
Cho, Won-Kyung [3 ,4 ]
机构
[1] Catholic Univ Korea, Daejeon St Marys Hosp, Coll Med, Dept Ophthalmol, Seoul, South Korea
[2] Catholic Univ Korea, Daejeon St Marys Hosp, Coll Med, Dept Pathol, Seoul, South Korea
[3] Catholic Univ Korea, Uijeongbu St Marys Hosp, Coll Med, Dept Ophthalmol, Seoul, South Korea
[4] Catholic Univ Korea, Uijeongbu St Marys Hosp, Coll Med, Dept Ophthalmol, 222 Banpo daero, Seoul, South Korea
关键词
congenital subconjunctival mass; epibulbar dermolipoma; epibulbar osseous choristoma;
D O I
10.1097/MD.0000000000031555
中图分类号
R5 [内科学];
学科分类号
1002 ; 100201 ;
摘要
Background:A choristoma is defined as a growth of histologically normal tissue in an abnormal location. Epibulbar osseous choristoma is the rarest type among all ocular choristoma with less than 100 cases reported. Here, we report a case of epibulbar osseous choristoma combined with dermolipoma and a literature review Methods:A 15-year-old female patient presented with an accidentally found subconjunctival mass in her left eye. Slit lamp examination revealed a 10 x 10 mm elevated, sigmoid-shaped mass in the supratemporal quadrant of the bulbar conjunctiva. We performed a debulking excisional biopsy of the mass. Results:The pathology confirmed osseous tissue surrounded by mature adipose tissue. At 1 week after the operation, the wound was clear and the patient was satisfied with the treatment. A systematic literature review of 14 previously published cases taken from PubMed dating back to 1987 along with ours was undertaken. The average age at presentation was 11.6 years and there was a female preponderance with 10 cases being female and the other 5 cases being male. Supratemporal conjunctiva was the most common site of presentation. There was no systemic disease associated with any of the cases. Since it is a benign tumor, it can be managed by observation, but if necessary, it can be treated by surgical removal. Conclusion:In pediatric subconjunctival mass, particularly located in supratemporal quadrant of bulbar conjunctiva, osseous choristoma should be considered in the differential diagnosis. Pre-operative CT scans will helpful to not also reduce complication with surgical excision but also helpful in prediction of diagnosis and prognosis.
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页数:4
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