Safety and efficacy of rozanolixizumab in patients with generalised myasthenia gravis (MycarinG): a randomised, double-blind, placebo-controlled, adaptive phase 3 study

被引:6
|
作者
Bril, Vera [1 ]
Druzdz, Artur [2 ]
Grosskreutz, Julian [3 ]
Habib, Ali A. [4 ]
Mantegazza, Renato [5 ]
Sacconi, Sabrina [6 ]
Utsugisawa, Kimiaki [7 ]
Vissing, John [8 ]
Vu, Tuan [9 ]
Boehnlein, Marion [10 ]
Bozorg, Ali [11 ]
Gayfieva, Maryam [12 ]
Greve, Bernhard [10 ]
Woltering, Franz [10 ]
Kaminski, Henry J. [13 ]
机构
[1] Univ Hlth Network, Toronto, ON, Canada
[2] Municipal Hosp, Dept Neurol, Poznan, Poland
[3] Univ Lubeck, Dept Neurol, Precis Neurol, Lubeck, Germany
[4] Univ Calif Irvine, MDA ALS & Neuromuscular Ctr, Irvine, CA USA
[5] Fdn Ist Ricovero & Cura Carattere Sci, Ist Nazl Neurol Carlo Besta, Milan, Italy
[6] Univ Cote Azur, Ctr Hosp Univ Nice, Pasteur Hosp 2, Peripheral Nervous Syst & Muscle Dept, Nice, France
[7] Hanamaki Gen Hosp, Dept Neurol, Hanamaki, Japan
[8] Univ Copenhagen, Copenhagen Neuromuscular Ctr, Dept Neurol, Rigshosp, Copenhagen, Denmark
[9] Univ S Florida, Dept Neurol, Morsani Coll Med, Tampa, FL USA
[10] UCB Pharm, Monheim, Germany
[11] UCB Pharm, Morrisville, NC USA
[12] UCB Pharm, Slough, England
[13] George Washington Univ, Washington, DC USA
来源
LANCET NEUROLOGY | 2023年 / 22卷 / 05期
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R74 [神经病学与精神病学];
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摘要
Background Generalised myasthenia gravis is a chronic, unpredictable, and debilitating autoimmune disease. New treatments for this disease are needed because conventional therapies have limitations, such as side-effects (eg, increased infection risk) or inadequate control of symptoms. Rozanolixizumab is a neonatal Fc receptor blocker that might provide a novel therapeutic option for myasthenia gravis. We aimed to assess the safety and efficacy of rozanolixizumab for generalised myasthenia gravis. Methods MycarinG is a randomised, double-blind, placebo-controlled, adaptive phase 3 study done at 81 outpatient centres and hospitals in Asia, Europe, and North America. We enrolled patients (aged >= 18 years) with acetylcholine receptor (AChR) or muscle-specific kinase (MuSK) autoantibody-positive generalised myasthenia gravis (Myasthenia Gravis Foundation of America class II-IVa), a Myasthenia Gravis Activities of Daily Living (MG-ADL) score of at least 3 (non-ocular symptoms), and a quantitative myasthenia gravis score of at least 11. Patients were randomly assigned (1:1:1) to receive subcutaneous infusions once a week for 6 weeks of either rozanolixizumab 7 mg/kg, rozanolixizumab 10 mg/kg, or placebo. Randomisation was stratified by AChR and MuSK autoantibody status. Investigators, patients, and people assessing outcomes were masked to random assignments. The primary efficacy endpoint was change from baseline to day 43 in MG-ADL score, assessed in the intention-to-treat population. Treatment-emergent adverse events (TEAEs) were assessed in all randomly assigned patients who received at least one dose of study drug. This trial is registered with ClinicalTrials.gov (NCT03971422) and EudraCT (2019-000968-18); an open-label extension study has been completed (NCT04124965; EudraCT 2019-000969-21) and another is underway (NCT04650854; EudraCT 2020003230-20). Findings Between June 3, 2019, and June 30, 2021, 300 patients were assessed for eligibility, of whom 200 were enrolled. 66 (33%) were randomly assigned to rozanolixizumab 7 mg/kg, 67 (34%) to rozanolixizumab 10 mg/kg, and 67 (34%) to placebo. Reductions in MG-ADL score from baseline to day 43 were greater in the rozanolixizumab 7 mg/kg group (least-squares mean change -3 center dot 37 [SE 0 center dot 49]) and in the rozanolixizumab 10 mg/kg group (-3 center dot 40 [0 center dot 49]) than with placebo (-0 center dot 78 [0 center dot 49]; for 7 mg/kg, least-squares mean difference -2 center dot 59 [95% CI -4 center dot 09 to -1 center dot 25], p<0 center dot 0001; for 10 mg/kg, -2 center dot 62 [-3 center dot 99 to -1 center dot 16], p<0 center dot 0001). TEAEs were experienced by 52 (81%) of 64 patients treated with rozanolixizumab 7 mg/kg, 57 (83%) of 69 treated with rozanolixizumab 10 mg/kg, and 45 (67%) of 67 treated with placebo. The most frequent TEAEs were headache (29 [45%] patients in the rozanolixizumab 7 mg/kg group, 26 [38%] in the rozanolixizumab 10 mg/kg group, and 13 [19%] in the placebo group), diarrhoea (16 [25%], 11 [16%], and nine [13%]), and pyrexia (eight [13%], 14 [20%], and one [1%]). Five (8%) patients in the rozanolixizumab 7 mg/kg group, seven (10%) in the rozanolixizumab 10 mg/kg group, and six (9%) in the placebo group had a serious TEAE. No deaths occurred. Interpretation Rozanolixizumab showed clinically meaningful improvements in patient-reported and investigator-assessed outcomes in patients with generalised myasthenia gravis, for both 7 mg/kg and 10 mg/kg doses. Both doses were generally well tolerated. These findings support the mechanism of action of neonatal Fc receptor inhibition in generalised myasthenia gravis. Rozanolixizumab represents a potential additional treatment option for patients with generalised myasthenia gravis.
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页码:383 / 394
页数:12
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