Langerhans cell histiocytosis of single-system multifocal bone, including the mandible, in a 22-month-old child: A case report

被引：0
|
作者：
Sakai, Kiyoshi [1 ]
Yamamoto, Noriyuki [1 ]
Yamaguchi, Satoshi [1 ]
Okabe, Kazuto [2 ]
Koma, Yoshiro [2 ]
Hibi, Hideharu [1 ,2 ]
机构：
[1] Nagoya Univ Hosp, Dept Oral & Maxillofacial Surg, Nagoya, Aichi, Japan
[2] Nagoya Univ, Dept Oral & Maxillofacial Surg, Grad Sch Med, Nagoya, Aichi, Japan
来源：
ORAL SCIENCE INTERNATIONAL | 2023年 / 20卷 / 01期
关键词：
bone lesions; Langerhans cell histiocytosis; mandible; single-system multi-site; tumor; EOSINOPHILIC GRANULOMA; RANDOMIZED TRIAL; THERAPY;
D O I：
10.1002/osi2.1147
中图分类号：
R78 [口腔科学];
学科分类号：
1003 ;
摘要：
Background: Langerhans cell histiocytosis (LCH) is a rare disease in which antigen-presenting Langerhans cells proliferate abnormally. Case Presentation: We report a case of a 22-month-old boy who presented with left cheek swelling. A palpable bony bulge was noted at the left mandibular angle and a malignant tumor was suspected. Computed tomography (CT) and magnetic resonance imaging (MRI) revealed an area of bone resorption from the left mandibular angle to the mandibular branch. Positron emission tomography (PET)-CT revealed accumulation in the left mandible, left femoral diaphysis, and L1 vertebra. The patient was diagnosed with multiple-bone LCH and underwent chemotherapy. Conclusion: Four years after treatment, the patient is doing well and has no recurrence.
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收藏
页码：60 / 64
页数：5
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