Immunology of Retinitis Pigmentosa and Gene Therapy-Associated Uveitis

被引:4
|
作者
Yang, Paul [1 ]
Mustafi, Debarshi [2 ,3 ,4 ]
Pepple, Kathryn L. [2 ]
机构
[1] Oregon Hlth & Sci Univ, Casey Eye Inst, Portland, OR 97239 USA
[2] Univ Washington, Roger & Karalis Johnson Retina Ctr, Dept Ophthalmol, Seattle, WA 98109 USA
[3] Brotman Baty Inst Precis Med, Seattle, WA 98109 USA
[4] Seattle Childrens Hosp, Dept Ophthalmol, Seattle, WA 98109 USA
来源
关键词
PHOTORECEPTOR CELL-DEATH; CHRONIC INFLAMMATORY REACTION; ADAPTIVE IMMUNE-RESPONSES; S-ANTIGEN REACTIVITY; RETINAL DEGENERATION; MOUSE MODEL; MYCOPHENOLATE-MOFETIL; MICROGLIAL ACTIVATION; ANIMAL-MODELS; MACULAR EDEMA;
D O I
10.1101/cshperspect.a041305
中图分类号
R-3 [医学研究方法]; R3 [基础医学];
学科分类号
1001 ;
摘要
The underlying immune state of inherited retinal degenerations (IRDs) and retinitis pigmentosa (RP) has been an emerging area of interest, wherein the consequences have never been greater given the widespread recognition of gene therapy-associated uveitis (GTU) in gene therapy clinical trials. Whereas some evidence suggests that the adaptive immune system may play a role, the majority of studies indicate that the innate immune system is likely the primary driver of neuroinflammation in RP. During retinal degeneration, discrete mechanisms activate resident microglia and promote infiltrating macrophages that can either be protective or detrimental to photoreceptor cell death. This persistent stimulation of innate immunity, overlaid by the introduction of viral antigens as part of gene therapy, has the potential to trigger a complex microglia/macrophage-driven proinflammatory state. A better understanding of the immune pathophysiology in IRD and GTU will be necessary to improve the success of developing novel treatments for IRDs.
引用
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页数:21
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