NF2-Related Schwannomatosis (NF2): Molecular Insights and Therapeutic Avenues

被引:2
|
作者
Kim, Bae-Hoon [1 ]
Chung, Yeon-Ho [1 ]
Woo, Tae-Gyun [1 ]
Kang, So-mi [2 ]
Park, Soyoung [2 ]
Kim, Minju [1 ]
Park, Bum-Joon [1 ,2 ]
机构
[1] PRG S&T Co Ltd, Rare Dis R&D Ctr, Busan 46274, South Korea
[2] Pusan Natl Univ, Coll Nat Sci, Dept Mol Biol, Busan 46241, South Korea
关键词
NF2; NF2-related schwannomatosis; Merlin; YAP; Yes-associated protein 1; RKIP; Raf kinase inhibitory protein; PPI; protein-protein interaction; INHIBITOR PROTEIN EXPRESSION; BILATERAL ACOUSTIC NEUROFIBROMATOSIS; HISTONE DEACETYLASE INHIBITOR; ENDOTHELIAL GROWTH-FACTOR; TUMOR-SUPPRESSOR GENE; VESTIBULAR SCHWANNOMAS; PHENOTYPE CORRELATIONS; CELL-PROLIFERATION; HIPPO PATHWAY; MERLIN;
D O I
10.3390/ijms25126558
中图分类号
Q5 [生物化学]; Q7 [分子生物学];
学科分类号
071010 ; 081704 ;
摘要
NF2-related schwannomatosis (NF2) is a genetic syndrome characterized by the growth of benign tumors in the nervous system, particularly bilateral vestibular schwannomas, meningiomas, and ependymomas. This review consolidates the current knowledge on NF2 syndrome, emphasizing the molecular pathology associated with the mutations in the gene of the same name, the NF2 gene, and the subsequent dysfunction of its product, the Merlin protein. Merlin, a tumor suppressor, integrates multiple signaling pathways that regulate cell contact, proliferation, and motility, thereby influencing tumor growth. The loss of Merlin disrupts these pathways, leading to tumorigenesis. We discuss the roles of another two proteins potentially associated with NF2 deficiency as well as Merlin: Yes-associated protein 1 (YAP), which may promote tumor growth, and Raf kinase inhibitory protein (RKIP), which appears to suppress tumor development. Additionally, this review discusses the efficacy of various treatments, such as molecular therapies that target specific pathways or inhibit neomorphic protein-protein interaction caused by NF2 deficiency. This overview not only expands on the fundamental understanding of NF2 pathophysiology but also explores the potential of novel therapeutic targets that affect the clinical approach to NF2 syndrome.
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页数:15
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